TY - JOUR
T1 - A novel murine model of autoimmune dysautonomia by α3 nicotinic acetylcholine receptor immunization
AU - Yamakawa, Makoto
AU - Nakane, Shunya
AU - Ihara, Eikichi
AU - Tawara, Nozomu
AU - Ikeda, Hiroko
AU - Igarashi, Yoko
AU - Komohara, Yoshihiro
AU - Takamatsu, Koutaro
AU - Ikeda, Tokunori
AU - Tomita, Yusuke
AU - Murai, Shoichi
AU - Ando, Yukio
AU - Mukaino, Akihiro
AU - Ogawa, Yoshihiro
AU - Ueda, Mitsuharu
N1 - Funding Information:
This study was supported by JSPS KAKENHI (Grant Numbers: 19K17012 and 19H03549).
Publisher Copyright:
Copyright © 2022 Yamakawa, Nakane, Ihara, Tawara, Ikeda, Igarashi, Komohara, Takamatsu, Ikeda, Tomita, Murai, Ando, Mukaino, Ogawa and Ueda.
PY - 2022/11/23
Y1 - 2022/11/23
N2 - We aimed to establish a novel murine model of autoimmune autonomic ganglionopathy (AAG), which represents autoimmune dysautonomia, associated with MHC class II to understand its pathomechanism and the pathogenicity of nicotinic acetylcholine receptor (nAChR) antibodies. The amino acid sequence of the mouse nAChRα3 protein was analyzed using an epitope prediction tool to predict the possible MHC class II binding mouse nAChRα3 peptides. We focused on two nAChRα3 peptides in the extracellular region, and experimental AAG (EAAG) was induced by immunization of C57BL/6 mice with these two different peptides. EAAG mice were examined both physiologically and histologically. Mice with EAAG generated nAChRα3 antibodies and exhibited autonomic dysfunction, including reduced heart rate, excessive fluctuations in systolic blood pressure, and intestinal transit slowing. Additionally, we observed skin lesions, such as alopecia and skin ulcers, in immunized mice. Neuronal cell density in the sympathetic cervical ganglia in immunized mice was significantly lower than that in control mice at the light microscopic level. We interpreted that active immunization of mice with nAChRα3 peptides causes autonomic dysfunction similar to human AAG induced by an antibody-mediated mechanism. We suggested a mechanism by which different HLA class II molecules might preferentially affect the nAChR-specific immune response, thus controlling diversification of the autoantibody response. Our novel murine model mimics AAG in humans and provides a useful tool to investigate its pathomechanism.
AB - We aimed to establish a novel murine model of autoimmune autonomic ganglionopathy (AAG), which represents autoimmune dysautonomia, associated with MHC class II to understand its pathomechanism and the pathogenicity of nicotinic acetylcholine receptor (nAChR) antibodies. The amino acid sequence of the mouse nAChRα3 protein was analyzed using an epitope prediction tool to predict the possible MHC class II binding mouse nAChRα3 peptides. We focused on two nAChRα3 peptides in the extracellular region, and experimental AAG (EAAG) was induced by immunization of C57BL/6 mice with these two different peptides. EAAG mice were examined both physiologically and histologically. Mice with EAAG generated nAChRα3 antibodies and exhibited autonomic dysfunction, including reduced heart rate, excessive fluctuations in systolic blood pressure, and intestinal transit slowing. Additionally, we observed skin lesions, such as alopecia and skin ulcers, in immunized mice. Neuronal cell density in the sympathetic cervical ganglia in immunized mice was significantly lower than that in control mice at the light microscopic level. We interpreted that active immunization of mice with nAChRα3 peptides causes autonomic dysfunction similar to human AAG induced by an antibody-mediated mechanism. We suggested a mechanism by which different HLA class II molecules might preferentially affect the nAChR-specific immune response, thus controlling diversification of the autoantibody response. Our novel murine model mimics AAG in humans and provides a useful tool to investigate its pathomechanism.
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U2 - 10.3389/fnins.2022.1006923
DO - 10.3389/fnins.2022.1006923
M3 - Article
AN - SCOPUS:85143410392
VL - 16
JO - Frontiers in Neuroscience
JF - Frontiers in Neuroscience
SN - 1662-4548
M1 - 1006923
ER -