Recurrent idiopathic pulmonary hemosiderosis after long-term remission presented with Sjogren's syndrome: Idiopathic no more?

Toyoshi Yanagihara, Yuzo Yamamoto, Naoki Hamada, Kunihiro Suzuki, Saiko Ogata-Suetsugu, Eiji Harada, Tetsuzo Tagawa, Minako Fujiwara, Mikiko Hashisako, Junya Fukuoka, Yoichi Nakanishi

Research output: Contribution to journalArticle

Abstract

We report a case of recurrent idiopathic pulmonary hemosiderosis after a long-term remission presented with Sjögren's syndrome. The patient was diagnosed with IPH due to repeated pneumonia and blood sputum in his childhood. He was admitted to our hospital due to exertional dyspnea and dry cough with bilateral ground-glass opacity in chest computed tomography at the age of 32. Video-assisted thoracoscopic surgery was performed and the specimens showed nonspecific interstitial pneumonia pattern with diffuse, chronic alveolar hemorrhage, suggesting recurrence of IPH. He was also diagnosed with Sjögren's syndrome. Further immunological studies will reveal the pathogenesis of IPH.

Original languageEnglish
Pages (from-to)68-72
Number of pages5
JournalRespiratory Medicine Case Reports
Volume25
DOIs
Publication statusPublished - Jan 1 2018

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Sjogren's Syndrome
Video-Assisted Thoracic Surgery
Interstitial Lung Diseases
Sputum
Cough
Dyspnea
Glass
Pneumonia
Thorax
Tomography
Hemorrhage
Recurrence
Idiopathic pulmonary hemosiderosis

All Science Journal Classification (ASJC) codes

  • Pulmonary and Respiratory Medicine

Cite this

Recurrent idiopathic pulmonary hemosiderosis after long-term remission presented with Sjogren's syndrome : Idiopathic no more? / Yanagihara, Toyoshi; Yamamoto, Yuzo; Hamada, Naoki; Suzuki, Kunihiro; Ogata-Suetsugu, Saiko; Harada, Eiji; Tagawa, Tetsuzo; Fujiwara, Minako; Hashisako, Mikiko; Fukuoka, Junya; Nakanishi, Yoichi.

In: Respiratory Medicine Case Reports, Vol. 25, 01.01.2018, p. 68-72.

Research output: Contribution to journalArticle

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