Spontaneous resolution of cystic hygroma and hydrops in a fetus with Noonan's syndrome

Asuka Kiyota; Kiyomi Tsukimori; Yasuo Yumoto; Satoshi Hojo; Seiichi Morokuma; Kotaro Fukushima; Yasushi Takahata; Hideki Nakayama; Norio Wake

doi:10.1159/000193364

Spontaneous resolution of cystic hygroma and hydrops in a fetus with Noonan's syndrome

Asuka Kiyota, Kiyomi Tsukimori, Yasuo Yumoto, Satoshi Hojo, Seiichi Morokuma, Kotaro Fukushima, Yasushi Takahata, Hideki Nakayama, Norio Wake

Division of Nursing

Research output: Contribution to journal › Article › peer-review

11 Citations (Scopus)

Abstract

Many studies have shown that the prognosis of cystic hygroma associated with hydrops fetalis is poor. We report a rare case of fetal cystic hygroma and hydrops fetalis that spontaneously resolved with subsequent delivery at 37 weeks of a living female infant with Noonan's syndrome. The prognostic significance of prenatal resolution of cystic hygroma and hydrops is uncertain. Serial evaluation of affected fetuses with ultrasound imaging may help clarify pathogenesis of cystic hygroma with associated hydrops, as well as mechanisms underlying spontaneous resolution.

Original language	English
Pages (from-to)	499-502
Number of pages	4
Journal	Fetal Diagnosis and Therapy
Volume	24
Issue number	4
DOIs	https://doi.org/10.1159/000193364
Publication status	Published - Jan 2009

All Science Journal Classification (ASJC) codes

Pediatrics, Perinatology, and Child Health
Embryology
Radiology Nuclear Medicine and imaging
Obstetrics and Gynaecology

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10.1159/000193364

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abstract = "Many studies have shown that the prognosis of cystic hygroma associated with hydrops fetalis is poor. We report a rare case of fetal cystic hygroma and hydrops fetalis that spontaneously resolved with subsequent delivery at 37 weeks of a living female infant with Noonan's syndrome. The prognostic significance of prenatal resolution of cystic hygroma and hydrops is uncertain. Serial evaluation of affected fetuses with ultrasound imaging may help clarify pathogenesis of cystic hygroma with associated hydrops, as well as mechanisms underlying spontaneous resolution.",

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AU - Kiyota, Asuka

AU - Tsukimori, Kiyomi

AU - Yumoto, Yasuo

AU - Hojo, Satoshi

AU - Morokuma, Seiichi

AU - Fukushima, Kotaro

AU - Takahata, Yasushi

AU - Nakayama, Hideki

AU - Wake, Norio

PY - 2009/1

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AB - Many studies have shown that the prognosis of cystic hygroma associated with hydrops fetalis is poor. We report a rare case of fetal cystic hygroma and hydrops fetalis that spontaneously resolved with subsequent delivery at 37 weeks of a living female infant with Noonan's syndrome. The prognostic significance of prenatal resolution of cystic hygroma and hydrops is uncertain. Serial evaluation of affected fetuses with ultrasound imaging may help clarify pathogenesis of cystic hygroma with associated hydrops, as well as mechanisms underlying spontaneous resolution.

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Spontaneous resolution of cystic hygroma and hydrops in a fetus with Noonan's syndrome

Abstract

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