Unilateral incontinentia pigmenti in a male infant

Chikage Mitoma, Ran Hidaka, Masutaka Furue

Research output: Contribution to journalArticle

Abstract

We report a unique case of unilateral incontinentia pigmenti in a male infant. Several days after birth, a few vesicles appeared on the right lower leg. After then, erythema with vesicles appeared, limited to the right inguinal area. Histopathological examination revealed eosinophilic spongiosis in the epidermis and an inflammatory cell infiltrate in company with scattered melanophages in the upper dermis. A thorough systemic examination did not show any other abnormalities of ectodermal organs, such as eyes, teeth, and central nervous systems. Based on all the results, we diagnosed the present case as a unilateral and mild case of incontinentia pigmenti. Herein we discuss the clinical features of male incontinentia pigmenti.

Original languageEnglish
Pages (from-to)214-216
Number of pages3
JournalNishinihon Journal of Dermatology
Volume77
Issue number3
DOIs
Publication statusPublished - Jan 1 2015

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Incontinentia Pigmenti
Groin
Erythema
Dermis
Epidermis
Leg
Tooth
Central Nervous System
Parturition

All Science Journal Classification (ASJC) codes

  • Dermatology

Cite this

Unilateral incontinentia pigmenti in a male infant. / Mitoma, Chikage; Hidaka, Ran; Furue, Masutaka.

In: Nishinihon Journal of Dermatology, Vol. 77, No. 3, 01.01.2015, p. 214-216.

Research output: Contribution to journalArticle

Mitoma, Chikage ; Hidaka, Ran ; Furue, Masutaka. / Unilateral incontinentia pigmenti in a male infant. In: Nishinihon Journal of Dermatology. 2015 ; Vol. 77, No. 3. pp. 214-216.
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